主页 文献库文献详情
PMID: 25500575 已发表 · ppublish 英语

Lethal neonatal rigidity and multifocal seizure syndrome--report of another family with a BRAT1 mutation.

Straussberg Rachel, Ganelin-Cohen Esther, Goldberg-Stern Hadassah, Tzur Shay, Behar Doron M, Smirin-Yosef Pola, Salmon-Divon Mali, Basel-Vanagaite Lina

摘要

We describe two siblings born to consanguineous Arab-Muslim parents who presented in early infancy with myoclonic seizures, hypertonia and contractures, arrested head growth, inability to swallow, and bouts of apnea-bradycardia, culminating in cardiac arrest and death. Whole-genome sequencing yielded a c.1173delG mutation in the BRAT1 gene. Three recent reports identified mutations in the same gene in three infants from three Amish sibships, one Mexican neonate and two Japanese siblings with similar clinical manifestations. The authors speculated that the destabilization of the encoded protein may underlie the catastrophic epilepsy and corticobasal neuronal degeneration. We suggest that BRAT1 be added to the growing list of genes that are related to severe early infantile (neonatal) epileptic encephalopathy.

关键词
Apnea Bradycardia Epilepsy Hypertonicity Infancy Seizures
文献信息
期刊
European journal of paediatric neurology : EJPN : official journal of the European Paediatric Neurology Society
期刊简称
Eur J Paediatr Neurol
发表日期
2016-04-01
收录日期
2015-02-14
更新日期
2015-02-14
语言
英语
国家/地区
England
NLM ID
9715169
分析服务
分析服务

联系地址

山东省济南市章丘区文博路2号

齐鲁师范学院 genelibs生信实验室

山东省济南市高新区舜华路750号

大学科技园北区F座4单元2楼

电话: 0531-88819269

微信公众号

关注微信订阅号,实时查看信息,关注医学生物学动态。


商务邮箱

E-mail: product@genelibs.com